Follicular ameloblastoma of maxilla is well known rare clinical entity known to be originated from odontogenic cells. Although ameloblastoma is developed from dental epithelial remnants, the presence of ameloblastoma in maxilla with epicenter from maxillary antrum and not at all from alveolar process is the rare phenomena. Here we report a rare presentation of this tumour as antrochoanal polyp with epicenter in maxillary antrum; in 45 year old lady who presented with unusual complaints of dry cough of six months duration along with hypothyroidism